
LH Moyes, B Majumder, DP Leiberman
Department of Vascular Surgery, Glasgow Royal Infirmary, 84 Castle Street, Glasgow, G4 0SF
Address for Correspondence: Miss LH Moyes Email: lisa_moyes@hotmail.com
SMJ 2007 52(4): 53
Graft-appendiceal
fistula is a rare variation of aorto-enteric fistula.
We report on the presentation and management of a 70-year-old lady who
presented ten years after an aortobifemoral graft with a discharging sinus in
her right groin. Investigations
suggested aortic graft infection and she was taken to theatre for a laparotomy.
An inflamed appendix with a necrotic tip was found in contact with the
aortic graft. The infected graft
was excised and an appendicectomy was performed.
The distal organs were revascularised with an axillobifemoral graft.
We review similar case reports.
Key words
The first case of aortoenteric fistula was described by Sir Astley
Cooper in 1829.1 With an
increasing number of aortic operations performed, the condition is now seen more
often and the incidence of fistula formation after aortic surgery is quoted as
0.5% and 1.6%.2, 3, 4 The
presentation of graft infection may be subtle when patients present with
gastrointestinal bleeding or vague abdominal pain, or more obvious when groin
sepsis or pseudoaneurysms are present. In
the majority of cases, the fistula involves the duodenum at the proximal
anastomosis (70%) although fistulation with the jejunum, ileum and colon have
been described.5 Graft
appendiceal fistula is a rare variation of aorto-enteric fistula, the first case
of eight being reported in 1969.6
We shall present a further case of a graft-appendiceal fistula with a
review of the literature.
A 70-year-old lady presented as an emergency with a three week history
of a tender swelling in her right groin. She
had an extensive vascular history, initially presenting 14 years previously with
bilateral claudication. She
underwent a left to right femoral-femoral crossover graft at that time but
eventually the graft failed and she had an aortobifemoral graft four years
later. She made a good recovery and
was symptom free for five years. Unfortunately
she complained of worsening claudication of the right leg and an angiogram
showed a right interface stenosis. A tube graft extension to the right profunda was carried out
with good result.
On admission to the vascular unit, she was found to have a discharging
sinus in her right groin. She was
afebrile and her admission bloods revealed haemoglobin of 11.6 g/dL, white cell
count of 8.7x109 and a CRP of 36.
A CT scan showed a cuff of inflammatory tissue around both limbs of the
graft with fluid around the right limb. This
suggested the diagnosis of aortic graft infection and she was taken to theatre
two days after admission for a laparotomy and exploration of the graft.
There was an inflammatory process around the right limb of the graft and
the tip of the appendix had become involved with the fibrous tissues surrounding
the aortic graft (Figure I).
An appendicectomy and excision of the bifurcation graft was carried out
and an axillobifemoral graft inserted using a Dacron prosthesis to revascularise
the distal limbs. Pathology of the
specimen confirmed acute inflammation of the appendix and peritonitis involving
the distal appendix with perforation at its tip.
Microbiological swabs from the groin and graft grew Streptococcus milleri
and Bacteroides. The patient made a
good recovery and was able to go home 14 days after her operation.
She is doing well at her six months from her surgery.
The
terms “aortic graft infection”, “acute appendicitis”, “aorto-enteric
fistula” and review of relevant references yielded 8 case reports in the
literature. Our patient was
included in the review. Details of the cases are summarised in Table I.
There
were nine cases of graft-appendiceal fistula in the literature including our own
case. The male to female ratio was 8:1 with a median age of 59
years (range 51 to 75 years). Four
patients had initial aortic surgery for aneurysm and five patients underwent
surgery for occlusive disease. The
median interval from initial operation to presentation with fistula was 7 years
(range 13 months and 17 years). Six
patients presented with intermittent minor rectal bleeding before they became
haemodynamically unstable with a significant bleed. Two patients complained of vague abdominal pain and three
patients had a pulsatile mass or evidence of groin sepsis.
Multiple investigations were executed before definitive surgery was
carried out. Five patients had an
upper gastrointestinal endoscopy with two barium enemas, three computed
tomography scans and three arteriograms performed.
This illustrates the lack of effectiveness of individual diagnostic
modalities and demonstrates the need for a high index of clinical suspicion in a
patient who presents with gastrointestinal bleeding or sepsis with history of
aortic reconstruction. At laparotomy there was a fistula between the appendix and
the right limb of the graft, often near the iliac anastomosis in each case.
Microbiological cultures were variable in eight cases with 50% showing no
growth and 50% infected with Escherichia coli, Enterococci or Staphylococcus
epidermidis. The management of the
patients with graft appendiceal fistula was varied and is summarised in Table I.
Two patients died, one of whom did not have complete excision of the
infected graft at initial operation. Significant
morbidity included myocardial infarction, deep venous thrombosis and below knee
amputation. Some patients were
followed up for up to seven years, and of the nine patients in the literature,
seven were well on review at clinic.
Discussion
Aortoenteric fistulae present a challenge to the vascular surgeon.
The presentation is often subtle and cases should be managed on an
individual basis. It is
thought that direct contact between the prosthesis and the gastrointestinal
tract is the initiating event, ultimately leading to fistula formation and graft
infection. Patients can present
with gastrointestinal bleeding, either intermittent rectal bleeding or if the
infection involves an anastomosis, massive haemorrhage with shock.
An infected graft can then develop pseudoaneurysms at any anastomosis or
give rise to evidence of sepsis either systemically or in the groin.7, 8 The literature suggests that gastrointestinal endoscopy is
the most useful diagnostic tool in patients who present with gastrointestinal
bleeding. Endoscopy may reveal an
erosion between the graft and the intestinal lumen, but can also exclude other
causes of bleeding from the upper GI tract.
However CT, MRI and more recently nuclear medicine studies also have a
role. Recent sensitivities and specificities for CT and nuclear positron
emission tomography studies in the diagnosis of graft infection are 74%, 86%,
91% and 64% respectively. MRI produces similar results to CT.9
The general consensus in the literature was that treatment should be
directed to removal of the appendix and complete graft excision with
revascularisation through non-infected tissue planes.10, 11
Conclusion
This
case report demonstrates that graft-appendiceal fistula is an unusual cause of
graft infection but it should be borne in mind when dealing with patients who
present with possible graft infection. The
most important management strategy is early diagnosis and complete excision of
the graft.
References
Cooper,
Sir Astley. Lectures on the
principles and practice of surgery. London,
Westley, 1829.
Sheil
AG, Reeve TS, Little JM et al. Aorto-intestinal
fistulas following operations on the abdominal aorta and iliac arteries.
British Journal of Surgery 1969; 56: 840-843.
Elliott JP,
Smith RF, Szilagyi DE. Aortoenteric
and paraprosthetic enteric fistulas: Problems of diagnosis and management.
Arch Surg 1974; 108: 479.
Alfrey
EJ, Stanton C, Dunnington G et al. Graft
appendiceal fistulas. J Vasc
Surg 1988; 7: 814-817.
Humphries
AW, Young JR, de Wolfe VG et al. Complications
of abdominal aortic surgery. Archives
of Surgery 1963, 86:43
Tyson
RR, Maier WP, DiPietrantonio S. Iliaco-appendiceal
fistula following Dacron aortic graft.
Am Surg 1969; 35(4): 241-243.
Dean
RH, Allen TR, Foster JH et al. Aortoduodenal
fistula: An uncommon but correctable cause of upper gastrointestinal
bleeding. Am Surg 1978; 44(1):
37-43.
Pipinos
II, Carr JA, Haithcock BE et al. Secondary
aortoenteric fistula. Annals of
Vascular Surgery 2000; 14(6): 688-696.
Fukuchi
K, Ishida Y, Higashi M et al. Detection
of aortic graft infection by fluorodeoxyglucose positron
emission tomography: comparison with computed tomographic findings. J Vas Surg 2005; 42(5): 919-925.
Kleinman
LH, Towne JB, Bernhard VM. A
diagnostic and therapeutic approach to aortoenteric fistulas: Clinical
experience with 20 patients. Surgery
1979; 86: 868-880.
Bunt
TJ. Synthetic vascular graft
infections: Graft enteric erosions and graft enteric fistulas.
Surgery 1983; 94: 1-9.
Risberg
B, Kewenter J. Arterio-appendiceal
fistula after arterial reconstruction with synthetic graft.
Acta Chir Scand 1978; 144: 121-123.
Krupski
WC, Mitchell A, Gewertz B et al. Appendicitis
and aortofemoral graft infection. Archives
of Surgery 1979; 114(8): 969.
Criado
FJ, Classen JN, Wilson TH Jn. Secondary
aorto-enteric fistulas: prosthetic and paraprosthetic.
American Surgeon 1981; 47: 313-321.
Kitzmiller
JW, Robb HJ, Barkel D et al. Iliac
appendiceal fistula: Case presentation and review of management.
J Vasc Surg 1984; 1: 695-696.
Moore-Gillon
V, Jarrett PE. Aorto-appendicular
fistula presenting with intermittent gastrointestinal bleeding.
J R Coll Surg Edin 1985; 30: 201-202.
Lauwers P, De Greef K, Van den Brande F et al. Aortic graft infection from appendicitis. A case report. Acta Chir Belg 2004; 104: 454-456.